© Springer Nature Switzerland AG 2021
C. S. Foster et al. (eds.)Uveitishttps://doi.org/10.1007/978-3-030-52974-1_68

68. Retinitis Pigmentosa

Jordan A. Ueberroth1  
(1)
Massachusetts Eye Research and Surgery Institution, Waltham, MA, USA
 
Keywords
Retinitis pigmentosaUveitis

Overview

  • Definition
    • A heterogeneous group of inherited retinal dystrophies primarily affecting the rod photoreceptors, with progressive involvement of the cone photoreceptors and retinal pigment epithelium
      • The most common form of inherited blindness

  • Symptoms
    • Nyctalopia

    • Ring scotoma
      • Typically with superior field affected first

      • Symmetric involvement (except in X-linked female carriers)

      • Slow and relentless progression

    • Metamorphopsia (from macular edema)

    • Late stage: dyschromatopsia and vision loss

  • Laterality
    • Bilateral

  • Course
    • Slow and relentless progression

  • Age of onset
    • First to second decade of life

  • Gender/race
    • Not applicable

  • Systemic association
    • Sensorineural hearing loss (30% of patients with retinitis pigmentosa [RP])

    • A variety of syndromes are associated with RP:
      • Usher syndrome, Bardet-Biedl syndrome, Senior Loken syndrome, adult Refsum disease, etc.

Exam: Ocular

Anterior Segment

  • Posterior subcapsular cataract

Posterior Segment

  • Bone spicules

  • Waxy optic disc pallor

  • Arteriolar attenuation

  • Cystoid macular edema

  • Disc drusen

  • Vitreous cells

Exam: Systemic

  • Hearing loss

Imaging

  • OCT
    • CME

    • Outer retinal atrophy

  • ERG
    • Flat or “extinguished”

  • Humphrey visual field (static automated perimetry) (HVF)
    • Ring scotoma, most notable on Goldmann kinetic perimetry

  • Fundus autofluorescence
    • Perifoveal hyperautofluorescent ring with midperipheral hypoautofluorescent spicules

Laboratory and Radiographic Testing

  • Genetic testing
    • Autosomal dominant RP: mild course with variable penetrance; mutations in rhodopsin and peripherin/RDS genes

    • Autosomal recessive RP: severe course with early onset

    • X-linked RP: very severe course with mutations in RPGR gene

Differential Diagnosis

  • Autoimmune retinopathy

  • Drug-induced retinal toxicity (e.g., thioridazine, chlorpromazine, chloroquine, hydroxychloroquine)

  • Pigmented paravenous retinochoroidal atrophy (PPRCA)

  • Rubella retinitis

  • Traumatic retinopathy

  • Syndromic pigmentary retinopathy
    • Including: Bardet-Biedl syndrome, Usher syndrome, Leber’s congenital amaurosis, neuronal ceroid lipofuscinosis, Kearns-Sayre syndrome, Batten disease, Refsum disease, abetalipoproteinemia, and Senior Loken syndrome.

  • Congenital stationary night blindness (CSNB)

  • Choroideremia

  • Stargardt maculopathy

  • Bietti crystalline dystrophy

  • Vitamin A or zinc deficiency

  • Syphilis

  • Diffuse unilateral subacute neuroretinitis (DUSN)

Treatment

  • Referral to low vision specialist

  • Limitation of ultraviolet (UV) light exposure

  • Cataract extraction

  • For CME: topical or oral carbonic anhydrase inhibitors; intravitreal triamcinolone

  • Dietary modification:
    • Vitamin A 15,000 IU daily

    • ± docosahexaenoic acid (DHA) 1200 mg daily

    • ± lutein 12–20 mg daily

Referral/Co-management

  • Low vision specialist

  • Genetic counseling